Clinical and hystopathological dilemmas in diagnosis of epitheloid hemangioma of maxillae-case report


Clinical and hystopathological dilemmas in diagnosis of epitheloid hemangioma of maxillae-case report


Mergime Prekazi Loxha1, Zana Agani1 *, Alban Olluri3, Fisnik Kurshumliu2, Sinan Rusinovci3

1University of Prishtina, Faculty of Medicine, Department of Oral and Maxillofacial Surgery
2University of Prishtina, Faculty of Medicine, Department of Hysthology
3Clinical University Center Of Prishtina, Department of Maxillofacial Surgery


American Journal of Geographical Research and Reviews

Epithelioid hemangioma (EH) is a rare benign tumor involving the blood vessels and surrounding epithelioid cells. Epitheloid hemangioma, also called histiocytoid hemangioma, angiolymphoid hyperplasia with eosinophilia (ALHE), is a very rare benign tumor in maxillofacial region. There is a controversy in regards to correct diagnosis of an epithelioid hemangioma (EH), particularly when arising in skeletal locations, because of aggressive clinical characteristics, including multifocal presentation and occasional lymph node involvement. Specifically, its distinction from epithelioid hemangio-endothelioma (EHE) has been controversial. In literature we did not find a case where EH involves maxilla. However, there are few cases reported in which EH involved maxillary sinus and nasal cavity.
We will present a case of 21 year old male, who came to our Department with a lesion in frontal maxillary region. He underwent surgery four times, wide excision, and with four different histopathology results. The last result was ephiteloid hemangioma with metaplastic bone formation – a very rare benign lesion in oral region, but clinically with very aggressive nature.


Keywords: Clinical and hystopathological dilemmas, epitheloid hemangioma of maxillae, case report

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How to cite this article:
Mergime Prekazi Loxha, Zana Agani, Alban Olluri, Fisnik Kurshumliu, Sinan Rusinovci.Clinical and hystopathological dilemmas in diagnosis of epitheloid hemangioma of maxillae-case report. International Journal of Dental Research and Reviews, 2018, 1:7. DOI: 10.28933/ijdrr-2018-11-0808


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